Abstract
We report a 52-year-old woman with primary aggressive B-cell lymphoma occurring as two isolated masses in the external auditory canal and middle ear cleft of the left ear, simultaneously. The patient presented with left ear pain, blockage, decreased hearing, and a mass in the external ear canal. Histopathological examination confirmed the diagnosis, and patient was treated with surgery, chemo & radiotherapy. Primary lymphoma is extremely rare in the ear. As per our knowledge, it's the first case reporting two isolated masses occurring simultaneously in the same ear.